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DTHD1

DTHD1

Death domain-containing protein 1; exact role in vision is unknown. Identified by Abu-Safieh et al. (2013) through autozygome analysis and exome sequencing in a consanguineous family with LCA and mild muscular dystrophy.

No Targeted Treatment Yet

Chromosomal Locus

4p14

Inheritance

Autosomal Recessive

Frequency

<1% of LCA cases

Key Clinical Features

  • 1No official LCA subtype number assigned
  • 2Protein function in retina not yet characterized
  • 3Identified in a single family with LCA and mild muscular dystrophy
  • 4c.2T-C mutation causes >4-fold reduction in protein abundance

Syndromic Associations

Patients with DTHD1 mutations should be monitored for potential involvement of other organs:

  • Mild to moderate muscular dystrophy (in the original family)